Saved in:
Bibliographic Details
Main Authors: Dang, Lauren Eyler, Tarp, Jens Magelund, Abrahamsen, Trine Julie, Kvist, Kajsa, Buse, John B, Petersen, Maya, van der Laan, Mark
Format: Preprint
Published: 2022
Subjects:
Online Access:https://arxiv.org/abs/2210.05802
Tags: Add Tag
No Tags, Be the first to tag this record!
_version_ 1866909987901538304
author Dang, Lauren Eyler
Tarp, Jens Magelund
Abrahamsen, Trine Julie
Kvist, Kajsa
Buse, John B
Petersen, Maya
van der Laan, Mark
author_facet Dang, Lauren Eyler
Tarp, Jens Magelund
Abrahamsen, Trine Julie
Kvist, Kajsa
Buse, John B
Petersen, Maya
van der Laan, Mark
contents Augmenting a randomized controlled trial (RCT) with external data may increase power at the risk of introducing bias. To select and analyze the experiment (RCT alone or combined with external data) with the optimal bias-variance tradeoff, we develop a novel experiment-selector cross-validated targeted maximum likelihood estimator for randomized-external data studies (ES-CVTMLE). This estimator utilizes two estimates of bias to determine whether to integrate external data based on 1) a function of the difference in conditional mean outcome under control between the RCT and combined experiments and 2) an estimate of the average treatment effect on a negative control outcome (NCO). We define the asymptotic distribution of the ES-CVTMLE under varying magnitudes of bias and construct confidence intervals by Monte Carlo simulation. We evaluate ES-CVTMLE compared to three other data fusion estimators in simulations and demonstrate the ability of ES-CVTMLE to distinguish biased from unbiased external controls in a real data analysis of the effect of liraglutide on glycemic control from the LEADER trial. The ES-CVTMLE has the potential to improve power while providing relatively robust inference for future hybrid RCT-external data studies.
format Preprint
id arxiv_https___arxiv_org_abs_2210_05802
institution arXiv
publishDate 2022
record_format arxiv
spellingShingle Experiment-selector cross-validated targeted maximum likelihood estimator for hybrid RCT-external data studies
Dang, Lauren Eyler
Tarp, Jens Magelund
Abrahamsen, Trine Julie
Kvist, Kajsa
Buse, John B
Petersen, Maya
van der Laan, Mark
Methodology
Augmenting a randomized controlled trial (RCT) with external data may increase power at the risk of introducing bias. To select and analyze the experiment (RCT alone or combined with external data) with the optimal bias-variance tradeoff, we develop a novel experiment-selector cross-validated targeted maximum likelihood estimator for randomized-external data studies (ES-CVTMLE). This estimator utilizes two estimates of bias to determine whether to integrate external data based on 1) a function of the difference in conditional mean outcome under control between the RCT and combined experiments and 2) an estimate of the average treatment effect on a negative control outcome (NCO). We define the asymptotic distribution of the ES-CVTMLE under varying magnitudes of bias and construct confidence intervals by Monte Carlo simulation. We evaluate ES-CVTMLE compared to three other data fusion estimators in simulations and demonstrate the ability of ES-CVTMLE to distinguish biased from unbiased external controls in a real data analysis of the effect of liraglutide on glycemic control from the LEADER trial. The ES-CVTMLE has the potential to improve power while providing relatively robust inference for future hybrid RCT-external data studies.
title Experiment-selector cross-validated targeted maximum likelihood estimator for hybrid RCT-external data studies
topic Methodology
url https://arxiv.org/abs/2210.05802